# Mirizzi syndrome with an unusual type of biliobiliary fistula—a case report

**Authors:** Tsutomu Kawaguchi, Tadao Itoh, Kazuhiro Yoshii, Eigo Otsuji

PMC · DOI: 10.1186/s40792-015-0052-2 · Surgical Case Reports · 2015-06-17

## TL;DR

This case report describes a rare Mirizzi syndrome with an unusual biliobiliary fistula and a successful two-step treatment approach.

## Contribution

The paper presents a novel staged treatment strategy for a rare type of biliobiliary fistula in Mirizzi syndrome.

## Key findings

- The patient had a solitary gallstone, atrophic gallbladder, and a Corlette type I biliobiliary fistula.
- A staged treatment involving mucosal incineration and gallbladder extirpation was successfully applied.
- The case highlights the need for careful diagnosis and tailored treatment in managing this rare condition.

## Abstract

Gallstone obstruction of the cystic duct, resulting in chronic cholecystitis and pressure necrosis leads to the formation of biliobiliary fistula (BBF). We herein reported a case of Mirizzi syndrome (MS) with an unusual type of BBF (Corlette type I) that was successfully managed by a staged treatment strategy. The patient was diagnosed with a solitary gallstone, marked atrophy of the gallbladder, and BBF and underwent mucosal incineration of the atrophic gallbladder and simple closure, followed by extirpation of gallbladder. Although an optimal treatment strategy has not yet been established for MS with BBF because of its rarity and anatomical variations in fistulas, the current treatment strategy may be applicable. In conclusion, clinicians need to carefully diagnose and evaluate chronic cholecystitis in MS with BBF and adopt an optimal treatment strategy to avoid the complication associated with this disease.

## Linked entities

- **Diseases:** Mirizzi syndrome (MONDO:0043330), chronic cholecystitis (MONDO:0002155)

## Full-text entities

- **Genes:** GPT (glutamic--pyruvic transaminase) [NCBI Gene 2875] {aka AAT1, ALT, ALT1, GPT1, SGPT}, CRP (C-reactive protein) [NCBI Gene 1401] {aka PTX1}, SLC17A5 (solute carrier family 17 member 5) [NCBI Gene 26503] {aka AST, ISSD, NSD, SD, SIALIN, SIASD}, LOC102724197 (inactive glutathione hydrolase 2) [NCBI Gene 102724197] {aka GGT2}
- **Diseases:** BBF (MESH:D005402), adhesion of gallbladder (MESH:D005705), epigastric pain (MESH:D010146), AOSC (MESH:D013969), ductal stenosis (MESH:D044584), fever (MESH:D005334), Corlette type I (MESH:D006969), MS (MESH:D057792), inflammation (MESH:D007249), jaundice (MESH:D007565), dilation of the intrahepatic bile duct (MESH:C531647), Gallstone obstruction of (MESH:D042882), cholecystitis (MESH:D002764), bile duct malignancy (MESH:D001650), inflammatory response syndrome (MESH:D018746), bile duct (MESH:D001649), common bile duct (MESH:D003137), malignancy (MESH:D009369), obstructive jaundice (MESH:D041781), obstruction of the bile duct (MESH:D002779), atrophy (MESH:D001284), pressure necrosis (MESH:D009336)
- **Chemicals:** bilirubin (MESH:D001663), BBF (-)
- **Species:** Homo sapiens (human, species) [taxon 9606]

## Full text

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## Figures

4 figures with captions in the complete paper: https://tomesphere.com/paper/PMC4560140/full.md

## References

10 references — full list in the complete paper: https://tomesphere.com/paper/PMC4560140/full.md

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Source: https://tomesphere.com/paper/PMC4560140