# Sacrococcygeal polymelia: A case report and literature review

**Authors:** Shiyas Mohammedali, Saif Badran, Sohail J. Quazi, Sara Iskeirjeh, Branavan Sivakumaar

PMC · DOI: 10.1016/j.jpra.2026.01.023 · 2026-01-23

## TL;DR

This case report describes a rare congenital condition called sacrococcygeal polymelia in an infant and discusses its surgical treatment and outcomes.

## Contribution

A new case report of sacrococcygeal polymelia with insights into surgical management and multidisciplinary care.

## Key findings

- The accessory limb was successfully excised with preservation of normal anatomy.
- Postoperative healing was uneventful with good cosmetic results.
- Multidisciplinary care is emphasized for effective treatment of this rare condition.

## Abstract

Polymelia, first described by Macewen in 1877, is a rare congenital disorder characterized by the presence of accessory limbs. This case report describes a 2-month-old infant with sacrococcygeal polymelia and reviews the literature on pathophysiology, clinical presentations, and surgical management. Following the initial assessment, imaging studies, and clinical evaluation, the accessory limb was excised while preserving normal anatomy. Postoperatively, the wounds healed well with acceptable cosmetic results. This case report highlights the importance of multidisciplinary care for the treatment of this rare condition through careful preoperative assessment and precise surgical techniques.

## Full-text entities

- **Genes:** SHH (sonic hedgehog signaling molecule) [NCBI Gene 6469] {aka HHG1, HLP3, HPE3, MCOPCB5, SMMCI, ShhNC}
- **Diseases:** malformations (MESH:C564254), equinus (MESH:D004863), coccygeal cysts (MESH:D003560), pelvic instability (MESH:D034161), urinary or fecal incontinence (MESH:D005242), fetiform teratoma (MESH:D013724), knee flexion deformity (MESH:D007718), neurological deficits (MESH:D009461), inherited disorders (MESH:D030342), congenital disorder (MESH:D009358), flexion contracture (MESH:D003286), clubfoot deformity (MESH:D003025), malformed hip (MESH:D025981), pre (MESH:D058246), leg length discrepancy (MESH:D007870), Sacrococcygeal polymelia (MESH:C537225), anomaly (MESH:D000013), congenital malformation (OMIM:163000), lower-limb duplication (MESH:D038061)
- **Chemicals:** sevoflurane (MESH:D000077149), CO2 (MESH:D002245), mutagenic drugs (-), rocuronium (MESH:D000077123), fentanyl (MESH:D005283), oxygen (MESH:D010100)
- **Species:** Homo sapiens (human, species) [taxon 9606]

## Figures

4 figures with captions in the complete paper: https://tomesphere.com/paper/PMC12961207/full.md

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Source: https://tomesphere.com/paper/PMC12961207